Osteogenesis Imperfecta Essay

459 Words1 Page

Osteogenesis imperfecta (OI) is a rare, inherited connective tissue disorder that results in bone fragility and spontaneous fractures. A dominantly inherited form of OI is commonly associated with mutations in genes coding for type I collagen. However, recessive forms of OI can occur due to mutations of collagen modifying genes such as cartilage-associated protein (CRTAP) and prolyl-3-hydroxylase 1 (LEPRE1, P3H1). CRTAP and P3H1 are part of a regulatory compound (which also includes Cyclophilin B) of type I collagen. The goal for this project was to generate a purified compound of CRTAP and P3H1 to acquire a crystal structure. Because CRTAP and P3H1 are mutually-dependent, each gene was cloned into one vector at different multiple cloning sites to co-express the proteins in bacteria. …show more content…

coli for testing of protein expression. Initial tests confirmed the expression of both proteins, with P3H1 being expressed in lower amounts compared to CRTAP. I will continue with Dr. Morello to conduct expression tests in different E. coli types until I obtain optimal expression of both proteins. Because patients with recessive forms of osteogenesis imperfecta typically have an incomplete CRTAP/P3H1 complex, an artificial drug is a possibility in the future for said patients to reestablish the function of the complex. Once the structure of the CRTAP/P3H1 complex is understood, similar components can be derived to reestablish the function of an incomplete CRTAP/P3H1 complex. A bacterial strain that can optimally express both CRTAP and P3H1 simultaneously is the current major stepping stone. Upon completion of a high expression of both CRTAP and P3H1, larger quantities of the CRTAP/P3H1 complex will need to be purified and analyzed for a crystal structure by a crystallographer, whom has already been contacted and informed of the project and

More about Osteogenesis Imperfecta Essay

Open Document